Diez S, Syed J, Müller H, Besendörfer M, Schellerer V (2020)
Publication Type: Journal article
Publication year: 2020
Book Volume: 66
Pages Range: 381-384
DOI: 10.1016/j.ijscr.2019.12.037
Introduction: Pyoderma gangrenosum (PG) is a rare condition in infants, children and adolescents. The postoperative variant of this rapidly progressive ulceration is known as Cullen gangrene. Only a few case reports of pediatric Cullen gangrene have been published. Presentation of case: We present a male infant (gestational age 31 + 6 weeks) with gastroschisis and intrauterine volvulus. After multiple operations due to his complex gastrointestinal malformation, the patient showed classical symptoms of postoperative PG (PPG) 4 weeks after birth. Diagnosis could be made early in an interdisciplinary approach, differentiating intraabdominal infection (vancomycin resistant enterococcus (VRE), candida albicans) from epifascial occurrence. Treatment with high-dose steroids and immunoglobulins was initiated immediately and led to rapid recovery. Discussion: The unusual combination of a complex gastrointestinal malformation and an intraabdominal infection with VRE and candida albicans made the diagnosis difficult. However, early diagnosis is crucial in the treatment of Cullen gangrene. Conclusion: This is the first case report of Cullen gangrene presenting in an infant (at 4 weeks of age).
APA:
Diez, S., Syed, J., Müller, H., Besendörfer, M., & Schellerer, V. (2020). Pediatric Cullen gangrene: Case report of postoperative pyoderma gangrenosum in a preterm infant with a complex gastrointestinal malformation. International Journal of Surgery Case Reports, 66, 381-384. https://doi.org/10.1016/j.ijscr.2019.12.037
MLA:
Diez, Sonja, et al. "Pediatric Cullen gangrene: Case report of postoperative pyoderma gangrenosum in a preterm infant with a complex gastrointestinal malformation." International Journal of Surgery Case Reports 66 (2020): 381-384.
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